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Elsunersen receives FDA Breakthrough Therapy Designation for SCN2A-DEE (gain-of-function).

The US FDA has granted Breakthrough Therapy Designation to elsunersen (PRAX-222), an investigational antisense oligonucleotide for seizures in SCN2A-DEE caused by gain-of-function variants.

FDA BREAKTHROUGH THERAPYANNOUNCED 22 JUNE 2026INVESTIGATIONAL · NOT APPROVED
News23 June 2026 · Source: Praxis Precision Medicines, 22 June 2026

The US Food and Drug Administration has granted Breakthrough Therapy Designation to elsunersen (PRAX-222), an investigational treatment for seizures associated with SCN2A developmental and epileptic encephalopathy (SCN2A-DEE) caused by gain-of-function variants. Praxis Precision Medicines announced the designation on 22 June 2026.

Elsunersen is an antisense oligonucleotide (ASO) designed to reduce SCN2A gene expression, targeting the underlying cause of the condition rather than the symptoms alone.

The designation was based on results from the EMBRAVE Part A trial, a randomised, sham-controlled Phase 1/2 study in nine children aged 2 to 12 with early-seizure-onset SCN2A-DEE.

EMBRAVE Part A results

What the trial reported.

Reported results from the randomised, sham-controlled Phase 1/2 study that supported the designation.


77%
Sham-adjusted reduction in monthly seizures
from baseline (p=0.015)
71%
Achieved a >50% reduction in seizures
among treated children
57%
Reached at least 28 days of seizure freedom
across the six-month treatment period
1 yr
Benefit sustained in open-label extension
for up to one year

Improvements across sleep, motor function, muscle tone, attention or neuropsychomotor development were reported in all treated children and none of those on sham.

Praxis reported that elsunersen was well tolerated, with no drug-related serious adverse events, no discontinuations, and no neuroinflammation signals at doses up to 8 mg. Most adverse events were mild to moderate.

Elsunersen now holds Breakthrough Therapy, Orphan Drug and Rare Pediatric Disease designations from the FDA, and Orphan Drug and PRIME designations from the European Medicines Agency.

The pivotal EMBRAVE3 study

The pivotal EMBRAVE3 study is enrolling around 30 patients under a single-arm, baseline-controlled design. All participants receive elsunersen for 24 weeks, followed by a further 24-week extension. The primary analysis measures the change from baseline in countable motor seizures. The programme is being run in collaboration with Ionis Pharmaceuticals and RogCon.

Important
Elsunersen is investigational. It has not been approved by any regulator, including the Therapeutic Goods Administration (TGA), and is not available outside the clinical trial. Breakthrough Therapy Designation is a pathway intended to expedite development and review; it is not an approval. This post is a research update, not medical advice.
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